Nasal mucocutaneous leishmaniasis – An unusual form of presentation

Authors

  • Isa Eloi Serviço de Otorrinolaringologia, Centro Hospitalar e Universitário de Coimbra, Portugal https://orcid.org/0000-0003-2328-8652
  • Nuno Dias Silva Serviço de Otorrinolaringologia, Centro Hospitalar e Universitário de Coimbra, Portugal
  • José Pedro Carneiro Serviço de Otorrinolaringologia, Centro Hospitalar e Universitário de Coimbra, Portugal
  • Filipa Vaz Carvalho Serviço de Otorrinolaringologia, Centro Hospitalar e Universitário de Coimbra, Portugal
  • João Carlos Ribeiro Serviço de Otorrinolaringologia, Centro Hospitalar e Universitário de Coimbra, Portugal https://orcid.org/0000-0002-1039-6358
  • António Carlos Miguéis Serviço de Otorrinolaringologia, Centro Hospitalar e Universitário de Coimbra, Portugal
  • Jorge Eva Miguéis Serviço de Otorrinolaringologia, Centro Hospitalar e Universitário de Coimbra, Portugal

DOI:

https://doi.org/10.34631/sporl.1084

Keywords:

leishmaniasis, mucocutaneous leishmaniasis, nasal leishmaniasis

Abstract

Leishmaniasis is caused by the protozoan parasite Leishmania which is transmitted through bites of infected female phlebotomine sandflies. There are 3 main forms – visceral, cutaneous and mucocutaneous, with mucosal affection being the rarest manifestation of the disease. The incidence in Portugal is considered hypoendemic.

We present a case of a 48 years old female, with complaints of nasal obstruction, epistaxis and irregular erythematous scaly plaques surrounding the nostrils. Histology of the nasal septum and skin revealed the presence of Leishmania-Donovan bodies. She was treated with amphotericin-B and itraconazole with clinical improvement and disappearance of lesions.

Mucocutaneous leishmaniasis preferably affects the nasal mucosa and if not diagnosed and treated in time can lead to cartilage destruction and dissemination of mucosal lesions to the nasopharynx, larynx, compromising the airway and even leading to disfigurement.

References

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Published

2023-03-16

How to Cite

Eloi, I., Silva, N. D., Carneiro, J. P. ., Carvalho, F. V., Ribeiro, J. C., Miguéis, A. C., & Miguéis, J. E. (2023). Nasal mucocutaneous leishmaniasis – An unusual form of presentation. Portuguese Journal of Otorhinolaryngology and Head and Neck Surgery, 61(1), 101–105. https://doi.org/10.34631/sporl.1084

Issue

Section

Case Report